"Baby rattle" pelvis dysplasia

Am J Med Genet. 2001 Apr 15;100(1):37-42.

Abstract

We report an apparently previously undescribed lethal skeletal dysplasia, clinically resembling achondrogenesis, but with distinct radiologic and chondro-osseous morphologic features. These comprise bifid distal ends of the long bones of the limbs, absent vertebral body ossification, a unique "baby rattle" pelvic configuration with tall and broad ilia, absent endochondral ossification, regions of mesenchymal cells within the resting cartilage, and abnormal mesenchymal ossification.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Achondroplasia / pathology*
  • Adult
  • Bone and Bones / abnormalities
  • Bone and Bones / chemistry
  • Bone and Bones / ultrastructure
  • Collagen / analysis
  • Fatal Outcome
  • Female
  • Fetal Death
  • Fetal Diseases / pathology*
  • Fetus / abnormalities
  • Humans
  • Immunohistochemistry
  • Microscopy, Electron
  • Pregnancy

Substances

  • Collagen