Craniofacial hyperostoses in Proteus syndrome -- a case report

J Craniomaxillofac Surg. 2004 Dec;32(6):391-4. doi: 10.1016/j.jcms.2004.06.007.

Abstract

Objective: Description of a patient with a rare syndrome leading to the partial overgrowth of craniofacial bones.

Case report: In a 17-year-old female patient with severe hyperostoses of the craniofacial bones asymmetric overgrowth of the right upper and left lower limbs, linear hyperpigmentation of the right arm and a history of regional lipomatosis were found. These manifestations were suggestive of Proteus syndrome. The management of the craniofacial involvement is described and a literature overview presented.

Conclusion: Proteus syndrome is a rare overgrowth syndrome probably related to a somatic mutation that involves craniofacial structures in about 30% of patients. Early diagnosis is required for adequate interdisciplinary treatment.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Adolescent
  • Diagnosis, Differential
  • Facial Bones / pathology*
  • Female
  • Follow-Up Studies
  • Humans
  • Hyperostosis / pathology*
  • Hyperpigmentation / pathology
  • Lipomatosis / pathology
  • Proteus Syndrome / pathology*