A genetic variation in inositol polyphosphate 4 phosphatase a enhances susceptibility to asthma

Am J Respir Crit Care Med. 2008 Apr 1;177(7):712-9. doi: 10.1164/rccm.200705-781OC. Epub 2008 Jan 10.

Abstract

Rationale: Microarray data from mouse studies have identified a number of genes to be differentially expressed in allergen-sensitized mice lungs.

Objectives: Taking leads from these datasets, we attempted to identify novel genes associated with atopic asthma in humans.

Methods: We performed family-based genetic association analysis on selected markers within or in proximity of 21 human homologs of genes short-listed from ovalbumin-sensitized mouse studies in the Gene Expression Omnibus database of the National Center for Biotechnology Information. Family-based and case-control studies were undertaken for fine mapping and functional variation analysis of INPP4A (inositol polyphosphate 4 phosphatase type I). Western blot analysis was performed to analyze INPP4A protein stability from human platelets.

Measurements and main results: Our genetic association studies of 21 human genes in 171 trios led to the identification of a biallelic repeat (rs3217304) in INPP4A, associated with atopic asthma (P = 0.009). Further studies using additional three single nucleotide polymorphisms (SNPs), +92031A/T, +92344C/T, and +131237C/T, and two microsatellite markers, D2S2311 and D2S2187, revealed significant genetic associations with loci +92031A/T (P = 0.0012) and +92344C/T (P = 0.004). A nonsynonymous SNP, +110832A/G (Thr/Ala), present within a sequence enriched with proline, glutamic acid, serine, and threonine (PEST), in proximity of these two loci, showed a significant association with atopic asthma (P = 0.0006). The association results were also replicated in an independent cohort of 288 patients and 293 control subjects (P = 0.004). PEST score and Western blot analyses indicated a functional role of this SNP in regulating INPP4A protein stability.

Conclusions: In our study, INPP4A was identified as a novel asthma candidate gene, whereby the +110832A/G (Thr/Ala) variant affected its stability and was significantly associated with asthma.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Asian People / genetics*
  • Asthma / epidemiology
  • Asthma / genetics*
  • Case-Control Studies
  • Chemokine CCL5 / blood
  • Family Health
  • Female
  • Genetic Predisposition to Disease
  • Humans
  • India / epidemiology
  • Male
  • Oligonucleotide Array Sequence Analysis
  • Phosphoric Monoester Hydrolases / genetics*
  • Polymorphism, Single Nucleotide*

Substances

  • Chemokine CCL5
  • Phosphoric Monoester Hydrolases
  • phosphatidylinositol-3,4-bisphosphate 4-phosphatase