Delayed diagnosis of cleidocranial dysplasia in an adult: a case report

Acta Med Acad. 2014;43(1):92-6. doi: 10.5644/ama2006-124.106.

Abstract

Objective: To describe a rare case of cleidocranial dysplasia, an autosomal dominant inherited disease involving the skeleton and teeth, with delayed diagnosis.

Case report: We report a 24-year-old man with cleidocranial dysplasia admitted with hearing loss, rhinolalia, dyspnea and fatigue. Partial absence of clavicles, a bell-shaped ribcage, an open frontal fontanel, unerupted permanent teeth and broad sutures were identified at radiographic examination.

Conclusion: Cleidocranial dysplasia is very rare, and is commonly missed or diagnosed late. Radiographic findings are essential for diagnosis. An open frontal fontanel is a particularly important finding for neurosurgeons in diagnosis. We describe this rare case and discuss the clinical features of CCD.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple / diagnostic imaging*
  • Adult
  • Clavicle / abnormalities
  • Clavicle / diagnostic imaging
  • Cleidocranial Dysplasia / complications
  • Cleidocranial Dysplasia / diagnostic imaging*
  • Delayed Diagnosis*
  • Diagnosis, Differential
  • Dyspnea / complications
  • Fatigue / complications
  • Hearing Loss / complications
  • Humans
  • Male
  • Tomography, X-Ray Computed / methods
  • Tooth Abnormalities / complications
  • Tooth Abnormalities / diagnosis
  • Tooth Abnormalities / diagnostic imaging
  • Young Adult